Abstract
Background: Presence of different cell lines in
the head and neck region allows for the rare
possibility of different neoplastic processes
occurring simultaneously. The occurrence of these
co-existing lesions could just be coincidental but
occasionally may be due to a local or systemic
cause. To the best of the authors’ knowledge, there
are no previous reports of co-existing ossifying
fibroma and pleomorphic adenoma in the head and
neck region in the English literature.
Case presentation: A 39-year old female
presented with a chief complaint of recurrent
swelling on the right side of the neck of nine years’
duration and left maxillary swelling of eight and a
half years duration both of which were spontaneous
in onset. The swellings had slowly increased in
size to the dimension at presentation with no other
significant findings in the medical and family
history. Following other relevant history,
examination and investigations a diagnosis of left
maxillary ossifying fibroma and right recurrent
parotid pleomorphic adenoma was made. Surgical
excision of the two lesions were done with good
outcome. We present a case of concurrent
ossifying fibroma and pleomorphic adenoma
occurring in the head and neck region. We also
discussed the most important features, biologic
behaviour and treatment of these two lesions and
reviewed the literature.
Conclusion: Although the co-existence of these
two lesions presented appear to be coincidental,
however, the possibility of an underlying systemic
link cannot be totally ruled out. Further reporting
of similar cases may help to throw more light for
better understanding of these multiple lesions.
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